Project 461541

Mechano-adaptation in Osteogenesis Imperfecta

461541

Mechano-adaptation in Osteogenesis Imperfecta

$868,276
Project Information
Study Type: Unclear
Research Theme: Biomedical
Institution & Funding
Principal Investigator(s): Willie, Bettina M; Rauch, Frank
Co-Investigator(s): Han, Hong; Mikolajewicz, Nicholas A; Tauer, Josephine T; Weinkamer, Richard
Institution: Shriners Hospital for Children (Montréal)
CIHR Institute: Musculoskeletal Health and Arthritis
Program: Project Grant
Peer Review Committee: Clinical Investigation - B: Arthritis, Bone, Skin and Cartilage
Competition Year: 2022
Term: 5 yrs 0 mth
Abstract Summary

Osteogenesis imperfecta is a rare disorder that results in frequent fractures and often requires orthopedic interventions. Our clinical studies show that the periosteal circumference is consistently low in children with osteogenesis imperfecta. A lack of bone formation at the outer surface of the bone is a key factor in long-bone fractures, but the causes of this deficiency have not been investigated. Since bone is highly responsive to mechanical loads, our overarching hypothesis is that genetic defects that lead to osteogenesis imperfecta may also lead to a lower than normal response to mechanical loading in the long-bone of individuals with this disease. We will investigate whether this disorder leads to an altered periosteal bone formation response to mechanical loading using mouse models of this disease.

No special research characteristics identified

This project does not include any of the advanced research characteristics tracked in our database.

Keywords
Bone Mechanical Forces Osteocytes Osteogenesis Imperfecta